TY - JOUR
T1 - Derepression of the Iroquois Homeodomain Transcription Factor Gene IRX3 Confers Differentiation Block in Acute Leukemia
AU - Somerville, Timothy
AU - Simeoni, Fabrizio
AU - Chadwick, John
AU - Williams, Emma
AU - Spencer, Gary
AU - Boros, Katalin
AU - Wirth, Christopher
AU - Tholouli, Eleni
AU - Byers, Richard
AU - Somervaille, Timothy
N1 - Funding Information:
We thank John Weightman, Jeff Barry, Toni Banyard, Abi Johnson, and staff at the Biological Resources Unit for technical assistance; Dan Wiseman for assistance with figures; and Ruud Delwel for sharing the survival data from the Dutch AML cohort. This work was supported by Cancer Research UK (grant C5759/A20971 ).
Publisher Copyright:
© 2018 The Authors
Copyright:
Copyright 2019 Elsevier B.V., All rights reserved.
PY - 2018/1/16
Y1 - 2018/1/16
N2 - The Iroquois homeodomain transcription factor gene IRX3 is expressed in the developing nervous system, limb buds, and heart, and transcript levels specify obesity risk in humans. We now report a functional role for IRX3 in human acute leukemia. Although transcript levels are very low in normal human bone marrow cells, high IRX3 expression is found in ∼30% of patients with acute myeloid leukemia (AML), ∼50% with T-acute lymphoblastic leukemia, and ∼20% with B-acute lymphoblastic leukemia, frequently in association with high-level HOXA gene expression. Expression of IRX3 alone was sufficient to immortalize hematopoietic stem and progenitor cells (HSPCs) in myeloid culture and induce lymphoid leukemias in vivo. IRX3 knockdown induced terminal differentiation of AML cells. Combined IRX3 and Hoxa9 expression in murine HSPCs impeded normal T-progenitor differentiation in lymphoid culture and substantially enhanced the morphologic and phenotypic differentiation block of AML in myeloid leukemia transplantation experiments through suppression of a terminal myelomonocytic program. Likewise, in cases of primary human AML, high IRX3 expression is strongly associated with reduced myelomonocytic differentiation. Thus, tissue-inappropriate derepression of IRX3 contributes significantly to the block in differentiation, which is the pathognomonic feature of human acute leukemias. Somerville et al. report that the Iroquois homeodomain transcription factor gene IRX3 is frequently derepressed in human acute leukemias of multiple lineages and contributes to the differentiation block, which is the pathognomonic feature of the disease.
AB - The Iroquois homeodomain transcription factor gene IRX3 is expressed in the developing nervous system, limb buds, and heart, and transcript levels specify obesity risk in humans. We now report a functional role for IRX3 in human acute leukemia. Although transcript levels are very low in normal human bone marrow cells, high IRX3 expression is found in ∼30% of patients with acute myeloid leukemia (AML), ∼50% with T-acute lymphoblastic leukemia, and ∼20% with B-acute lymphoblastic leukemia, frequently in association with high-level HOXA gene expression. Expression of IRX3 alone was sufficient to immortalize hematopoietic stem and progenitor cells (HSPCs) in myeloid culture and induce lymphoid leukemias in vivo. IRX3 knockdown induced terminal differentiation of AML cells. Combined IRX3 and Hoxa9 expression in murine HSPCs impeded normal T-progenitor differentiation in lymphoid culture and substantially enhanced the morphologic and phenotypic differentiation block of AML in myeloid leukemia transplantation experiments through suppression of a terminal myelomonocytic program. Likewise, in cases of primary human AML, high IRX3 expression is strongly associated with reduced myelomonocytic differentiation. Thus, tissue-inappropriate derepression of IRX3 contributes significantly to the block in differentiation, which is the pathognomonic feature of human acute leukemias. Somerville et al. report that the Iroquois homeodomain transcription factor gene IRX3 is frequently derepressed in human acute leukemias of multiple lineages and contributes to the differentiation block, which is the pathognomonic feature of the disease.
KW - HOXA9
KW - IRX3
KW - acute lymphoblastic leukemia
KW - acute myeloid leukemia
UR - http://www.scopus.com/inward/record.url?scp=85041674280&partnerID=8YFLogxK
U2 - 10.1016/j.celrep.2017.12.063
DO - 10.1016/j.celrep.2017.12.063
M3 - Article
C2 - 29346763
VL - 22
SP - 638
EP - 652
JO - Cell Reports
JF - Cell Reports
IS - 3
ER -